An Infected Giant Lymphangioma in a Child

Bülbül Acar, Serra; Kara, Manolya; Hançerli Törün, Selda; Öcal Demir, Sevliya; Tuğcu, Deniz; Karakaş, Zeynep; Çalışkan, Emine; Salman, Nuran; Somer, Ayper

doi:https://dx.doi.org/10.5222/j.child.2016.032

Case Report

DOI :10.5222/j.child.2016.032 IUP :10.5222/j.child.2016.032 Full Text (PDF)

An Infected Giant Lymphangioma in a Child

Serra Bülbül Acar, Manolya Kara, Selda Hançerli Törün, Sevliya Öcal Demir, Deniz Tuğcu, Zeynep Karakaş, Emine Çalışkan, Nuran Salman, Ayper Somer

Introduction: Lymphangiomas are rare congenital proliferations of lymphatic system. Complications like infection, hemorrhage, necrosis related to compression in adjacent tissue can be seen during the follow-up of giant lymphangiomas. Herein, we present a child case with infected giant lymphangioma on his right arm. Case Report: A 4.5- year- old girl with the prenatal diagnosis of cystic lymphangioma presented with redness, swelling and hyperemia on her right arm. She was illappeared at admission and had a fever of 38.5°C. There was a diffuse, and marked swelling of the right forearm associated with increased fever and hyperemia and an ulcerated lesion on anterior, and lateral wall of the right hemithorax. Laboratory examination revealed neutrophilic leucocytosis and an increase in acute phase reactants. Ultrasonographic examination was consistent with infected lymphangioma and she was started on ampicillinsulbactam treatment. Mangetic resonance imaging of right exremity, thorax and abdomen revealed multiseptate, hemorhagic and infected macrocystic lymphangioma unrelated with another macrocystic lymphangioma 3 cm in diameter on her right chest. Her fever persisted and her antibiotherapy was switched to teicoplanin and meropenem since her swab sample culture yielded growth of methicillin- resistant coagulase-negative staphylococcus growth. Because of its sclerosing effect intralesional tetracycline was administered after consultation with plastic surgery. Sirolimus (mTOR inhibitor) treatment was started after the control of infection was achieved. Conclusions: Multidisciplinary approach is warranted for children with lymphangiomas since they can be complicated and can accompany genetic syndromes.

Keywords: Giant lymphangioma, infection, child

DOI :10.5222/j.child.2016.032 IUP :10.5222/j.child.2016.032 Full Text (PDF)

Bir Çocuk Vakada Enfekte Dev Lenfanjiom

Serra Bülbül Acar, Manolya Kara, Selda Hançerli Törün, Sevliya Öcal Demir, Deniz Tuğcu, Zeynep Karakaş, Emine Çalışkan, Nuran Salman, Ayper Somer

Amaç: Lenfanjiyomlar, lenfatik sistemin ender görülen konjenital proliferasyonudur. Dev lenfanjiomların seyri sırasında enfeksiyon, kanama, komşu dokularda destrüksiyona bağlı nekroz gibi komplikasyonlar gelişebilir. Burada sağ kolundaki dev lenfanjiyomu enfekte olmuş bir çocuk vaka sunulmuştur. Vaka Sunumu: Prenatal kistik lenfanjioma tanılı 4.5 yaşında kız hasta, sağ kolda şişlik, kızarıklık ve ısı artışı ile getirildi. Başvuru anında genel durumu düşkün olan hastanın ateşi 38.5°C idi. Fizik muayenesinde sağ üst ekstremitede üst kolda belirgin olmak üzere yaygın, ısı artışı ve hipereminin eşlik ettiği şişlik ile sağ toraks ön ve yan duvarında ülsere lezyon mevcuttu. Laboratuvar incelemede nötrofil hakimiyetinde lökositozu ve akut faz yüksekliği izlendi. Ultrasonografi incelemesi enfekte lenfanjiyom ile uyumlu bulunan hastaya ampisilin-sulbaktam tedavisi başlandı. Çekilen üst ekstremite ve toraks-batın manyetik rezonans görüntüleme (MRG)’de sağ kolda seviyelenme veren, multiseptalı, hemorajik ve enfekte makrokistik lenfanjiom, toraksda en kalını 3 cm çapta makrokistik, birbiriyle ilişkisiz lenfanjiom saptandı. Ateşleri devam eden hastanın yara sürüntüsünden gönderilen kültürde metisilin dirençli koagülaz negatif stafilokok üremesi üzerine antibiyoterapisi teikoplaninmeropenem olarak düzenlendi. Plastik cerrahi ile konsülte edilen hastaya sklerozan etkisi nedeniyle lezyon içi tetrasiklin uygulandı. Enfeksiyonu kontrol altına alındıktan sonra mTOR inhibitörü (sirolimus) başlanan hasta izleme alındı. Sonuç: Lenfanjiyomlar, komplike olabilmeleri ve sendromlara eşlik edebilmeleri nedeniyle multidisipliner takip gerektirmektedir.

Keywords: Dev lenfanjiyom, enfeksiyon, çocuk

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APA

Bülbül Acar, S., Kara, M., Hançerli Törün, S., Öcal Demir, S., Tuğcu, D., Karakaş, Z., Çalışkan, E., Salman, N., & Somer, A. (2016). An Infected Giant Lymphangioma in a Child. Journal of Child, 16(1), 32-35. https://doi.org/10.5222/j.child.2016.032

AMA

Bülbül Acar S, Kara M, Hançerli Törün S, Öcal Demir S, Tuğcu D, Karakaş Z, Çalışkan E, Salman N, Somer A. An Infected Giant Lymphangioma in a Child. Journal of Child. 2016;16(1):32-35. https://doi.org/10.5222/j.child.2016.032

ABNT

Bülbül Acar, S.; Kara, M.; Hançerli Törün, S.; Öcal Demir, S.; Tuğcu, D.; Karakaş, Z.; Çalışkan, E.; Salman, N.; Somer, A. An Infected Giant Lymphangioma in a Child. Journal of Child, [Publisher Location], v. 16, n. 1, p. 32-35, 2016.

Chicago: Author-Date Style

Bülbül Acar, Serra, and Manolya Kara and Selda Hançerli Törün and Sevliya Öcal Demir and Deniz Tuğcu and Zeynep Karakaş and Emine Çalışkan and Nuran Salman and Ayper Somer. 2016. “An Infected Giant Lymphangioma in a Child.” Journal of Child 16, no. 1: 32-35. https://doi.org/10.5222/j.child.2016.032

Chicago: Humanities Style

Bülbül Acar, Serra, and Manolya Kara and Selda Hançerli Törün and Sevliya Öcal Demir and Deniz Tuğcu and Zeynep Karakaş and Emine Çalışkan and Nuran Salman and Ayper Somer. “An Infected Giant Lymphangioma in a Child.” Journal of Child 16, no. 1 (Jun. 2025): 32-35. https://doi.org/10.5222/j.child.2016.032

Harvard: Australian Style

Bülbül Acar, S & Kara, M & Hançerli Törün, S & Öcal Demir, S & Tuğcu, D & Karakaş, Z & Çalışkan, E & Salman, N & Somer, A 2016, 'An Infected Giant Lymphangioma in a Child', Journal of Child, vol. 16, no. 1, pp. 32-35, viewed 5 Jun. 2025, https://doi.org/10.5222/j.child.2016.032

Harvard: Author-Date Style

Bülbül Acar, S. and Kara, M. and Hançerli Törün, S. and Öcal Demir, S. and Tuğcu, D. and Karakaş, Z. and Çalışkan, E. and Salman, N. and Somer, A. (2016) ‘An Infected Giant Lymphangioma in a Child’, Journal of Child, 16(1), pp. 32-35. https://doi.org/10.5222/j.child.2016.032 (5 Jun. 2025).

MLA

Bülbül Acar, Serra, and Manolya Kara and Selda Hançerli Törün and Sevliya Öcal Demir and Deniz Tuğcu and Zeynep Karakaş and Emine Çalışkan and Nuran Salman and Ayper Somer. “An Infected Giant Lymphangioma in a Child.” Journal of Child, vol. 16, no. 1, 2016, pp. 32-35. [Database Container], https://doi.org/10.5222/j.child.2016.032

Vancouver

Bülbül Acar S, Kara M, Hançerli Törün S, Öcal Demir S, Tuğcu D, Karakaş Z, Çalışkan E, Salman N, Somer A. An Infected Giant Lymphangioma in a Child. Journal of Child [Internet]. 5 Jun. 2025 [cited 5 Jun. 2025];16(1):32-35. Available from: https://doi.org/10.5222/j.child.2016.032 doi: 10.5222/j.child.2016.032

ISNAD

Bülbül Acar, Serra - Kara, Manolya - Hançerli Törün, Selda - Öcal Demir, Sevliya - Tuğcu, Deniz - Karakaş, Zeynep - Çalışkan, Emine - Salman, Nuran - Somer, Ayper. “An Infected Giant Lymphangioma in a Child”. Journal of Child 16/1 (Jun. 2025): 32-35. https://doi.org/10.5222/j.child.2016.032

Volume 16, Issue 12016, P. 32-35

TIMELINE

Submitted	22.03.2017
Accepted	25.05.2017

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Journal of Child

Case Report

An Infected Giant Lymphangioma in a Child

Bir Çocuk Vakada Enfekte Dev Lenfanjiom

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