Journal of Child

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Research Article


DOI :10.5222/j.child.2010.100   IUP :10.5222/j.child.2010.100    Full Text (PDF)

A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly

Nalan Karabayır, Selvinaz Edizer, Servet Erdal Adal, Güldemet Kaya, Sultan Kaba

Aortic arch abnormalities which emerge as a result of the abnormal regression of the bronchial arch system during fetal life, may completely or partially surround the trachea and/or esophagus leading to respiratory system symptoms. Such abnormalities may cause a severe respiratory distress immediately after birth or can remain asymptomatic during the entire life period of the individual. However, many children with a vascular ring anomaly may present with dyspnea, coughing, lung infections, stridor or dysphagia. An increasing inspiratory stridor and cyanosis developed in a term neonate, after a feeding event. He had been hospitalized with diagnosis of pneumoniae showing signs of respiratory distress and feeding difficulty. Laryngoscopic examination revealed normal findings, but an echocardiogram of the infant demonstrated an aortic arch abnormality. Barium scan displayed an indentation on the esophagus and a HRCT confirmed the diagnosis of a double aortic arch, and the baby was operated. He is currently followed at the outpatient clinic as his symptoms disappeared after surgery. In conclusion, respiratory system symptoms in neonates, particularly when a stridor event is present, must make us consider vascular ring abnormality in the differential diagnosis.

Keywords: Respiartory distress, newborn, vasculary ring
DOI :10.5222/j.child.2010.100   IUP :10.5222/j.child.2010.100    Full Text (PDF)

Yenidoğanda Solunum Sıkıntısının Ender Bir Nedeni: Vasküler Ring Anomalisi

Nalan Karabayır, Selvinaz Edizer, Servet Erdal Adal, Güldemet Kaya, Sultan Kaba

Embriyolojik olarak fetal yaşamda bronşial ark sisteminin anormal regresyonu sonucu ortaya çıkan aortik ark anomalileri trakea ve/veya özofagusu tam ya da inkomplet olarak sararak solunum sistemi semptomlarına neden olabilir. Bu anomaliler doğumdan hemen sonra ortaya çıkan ağır solunum sıkıntısına neden olabileceği gibi yaşam boyu asemptomatik de olabilir. Ancak, vasküler ring anomalisi olan pek çok çocuk dispne, öksürük, yineleyen akciğer infeksiyonları, stridor ya da disfaji ile gelir. İki günlük term erkek bebek solunum sıkıntısı ve emmeme yakınmalarıyla yenidoğan servisine yatırıldı. Fizik muayenede hışıltısı olan vakanın akciğer grafisinde infiltrasyon görülmesi ve infeksiyon göstergelerinin pozitif olması nedeniyle pnömoni tanısı konarak antibiyoterapi başlandı. İlerleyen günlerde hışıltı yanında özellikle beslenmeden sonra belirginleşen inspiratuar stridor ve siyanozu ortaya çıktı. Laringeal anomalileri dışlamak amacıyla yapılan KBB muayenesi normal olan vakanın ekokardiyogramında aortik ark anomalisi olabileceği düşünüldü. Baryumlu grafide özofagus basısının görülmesi üzerine çekilen HRCT’de “double aortik ark” tanısı kesinleştirilen hasta operasyona verildi. Operasyon sonrası semptomları ortadan kalkan hasta halen ayaktan izlenmektedir. Yenidoğanda özellikle stridor varlığında vasküler ring anomalisi ayırıcı tanıda düşünülmelidir.

Keywords: Solunum sıkıntısı, vasküler ring, yenidoğan

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APA

Karabayır, N., Edizer, S., Adal, S.E., Kaya, G., & Kaba, S. (2010). A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly. Journal of Child, 10(2), 100-102. https://doi.org/10.5222/j.child.2010.100


AMA

Karabayır N, Edizer S, Adal S E, Kaya G, Kaba S. A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly. Journal of Child. 2010;10(2):100-102. https://doi.org/10.5222/j.child.2010.100


ABNT

Karabayır, N.; Edizer, S.; Adal, S.E.; Kaya, G.; Kaba, S. A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly. Journal of Child, [Publisher Location], v. 10, n. 2, p. 100-102, 2010.


Chicago: Author-Date Style

Karabayır, Nalan, and Selvinaz Edizer and Servet Erdal Adal and Güldemet Kaya and Sultan Kaba. 2010. “A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly.” Journal of Child 10, no. 2: 100-102. https://doi.org/10.5222/j.child.2010.100


Chicago: Humanities Style

Karabayır, Nalan, and Selvinaz Edizer and Servet Erdal Adal and Güldemet Kaya and Sultan Kaba. “A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly.” Journal of Child 10, no. 2 (Nov. 2024): 100-102. https://doi.org/10.5222/j.child.2010.100


Harvard: Australian Style

Karabayır, N & Edizer, S & Adal, SE & Kaya, G & Kaba, S 2010, 'A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly', Journal of Child, vol. 10, no. 2, pp. 100-102, viewed 15 Nov. 2024, https://doi.org/10.5222/j.child.2010.100


Harvard: Author-Date Style

Karabayır, N. and Edizer, S. and Adal, S.E. and Kaya, G. and Kaba, S. (2010) ‘A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly’, Journal of Child, 10(2), pp. 100-102. https://doi.org/10.5222/j.child.2010.100 (15 Nov. 2024).


MLA

Karabayır, Nalan, and Selvinaz Edizer and Servet Erdal Adal and Güldemet Kaya and Sultan Kaba. “A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly.” Journal of Child, vol. 10, no. 2, 2010, pp. 100-102. [Database Container], https://doi.org/10.5222/j.child.2010.100


Vancouver

Karabayır N, Edizer S, Adal SE, Kaya G, Kaba S. A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly. Journal of Child [Internet]. 15 Nov. 2024 [cited 15 Nov. 2024];10(2):100-102. Available from: https://doi.org/10.5222/j.child.2010.100 doi: 10.5222/j.child.2010.100


ISNAD

Karabayır, Nalan - Edizer, Selvinaz - Adal, ServetErdal - Kaya, Güldemet - Kaba, Sultan. “A Rare Cause of Respiratory Distress in the Newborn: Vascular Ring Anomaly”. Journal of Child 10/2 (Nov. 2024): 100-102. https://doi.org/10.5222/j.child.2010.100



TIMELINE


Published Online30.12.2010

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